The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey

dc.contributor.authorKersten, Casper M.
dc.contributor.authorHermelijn, Sergei M.
dc.contributor.authorMullassery, Dhanya
dc.contributor.authorMuthialu, Nagarajan
dc.contributor.authorCobanoglu, Nazan
dc.contributor.authorGartner, Silvia
dc.contributor.authorBagolan, Pietro
dc.contributor.authorMesas Burgos, Carmen
dc.contributor.authorSgrò, Alberto
dc.contributor.authorHeyman, Stijn
dc.contributor.authorTill, Holger
dc.contributor.authorSuominen, Janne
dc.contributor.authorSchurink, Maarten
dc.contributor.authorDesender, Liesbeth
dc.contributor.authorLosty, Paul
dc.contributor.authorSteyaert, Henri
dc.contributor.authorTerheggen-Lagro, Suzanne
dc.contributor.authorMetzelder, Martin
dc.contributor.authorBonnard, Arnaud
dc.contributor.authorSfeir, Rony
dc.contributor.authorSingh, Michael
dc.contributor.authorYardley, Iain
dc.contributor.authorRikkers-Mutsaerts, Noor R. V. M.
dc.contributor.authorvan der Ent, Cornelis K.
dc.contributor.authorQvist, Niels
dc.contributor.authorCox, Des W.
dc.contributor.authorPeters, Robert
dc.contributor.authorBannier, Michiel A. G. E.
dc.contributor.authorWessel, Lucas
dc.contributor.authorProesmans, Marijke
dc.contributor.authorStanton, Michael
dc.contributor.authorHannon, Edward
dc.contributor.authorZampoli, Marco
dc.contributor.authorMorini, Francesco
dc.contributor.authorTiddens, Harm A. W. M.
dc.contributor.authorWijnen, René M. H.
dc.contributor.authorSchnater, Johannes M.
dc.date.accessioned2024-02-21T10:26:57Z
dc.date.available2024-02-21T10:26:57Z
dc.date.issued2022-07-30
dc.date.updated2022-08-25T11:18:02Z
dc.description.abstractConsensus on the optimal management of asymptomatic congenital pulmonary airway malformation (CPAM) is lacking, and comparison between studies remains difficult due to a large variety in outcome measures. We aimed to define a core outcome set (COS) for pediatric patients with an asymptomatic CPAM. An online, three-round Delphi survey was conducted in two stakeholder groups of specialized caregivers (surgeons and non-surgeons) in various European centers. Proposed outcome parameters were scored according to level of importance, and the final COS was established through consensus. A total of 55 participants (33 surgeons, 22 non-surgeons) from 28 centers in 13 European countries completed the three rounds and rated 43 outcome parameters. The final COS comprises seven outcome parameters: respiratory insufficiency, surgical complications, mass effect/mediastinal shift (at three time-points) and multifocal disease (at two time-points)<b>.</b> The seven outcome parameters included in the final COS reflect the diversity in priorities among this large group of European participants. However, we recommend the incorporation of these outcome parameters in the design of future studies, as they describe measurable and validated outcomes as well as the accepted age at measurement.
dc.identifierdoi: 10.3390/children9081153
dc.identifier.apacitationKersten, Casper M., Hermelijn, Sergei M., Mullassery, D., Muthialu, N., Cobanoglu, N., Gartner, S., ... Schnater, Johannes M. (2022). The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey. <i>Children</i>, http://hdl.handle.net/11427/39147en_ZA
dc.identifier.chicagocitationKersten, Casper M., Sergei M. Hermelijn, Dhanya Mullassery, Nagarajan Muthialu, Nazan Cobanoglu, Silvia Gartner, Pietro Bagolan, et al "The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey." <i>Children</i> (2022) http://hdl.handle.net/11427/39147en_ZA
dc.identifier.citationChildren 9 (8): 1153 (2022)
dc.identifier.ris TY - Journal Article AU - Kersten, Casper M. AU - Hermelijn, Sergei M. AU - Mullassery, Dhanya AU - Muthialu, Nagarajan AU - Cobanoglu, Nazan AU - Gartner, Silvia AU - Bagolan, Pietro AU - Mesas Burgos, Carmen AU - Sgrò, Alberto AU - Heyman, Stijn AU - Till, Holger AU - Suominen, Janne AU - Schurink, Maarten AU - Desender, Liesbeth AU - Losty, Paul AU - Steyaert, Henri AU - Terheggen-Lagro, Suzanne AU - Metzelder, Martin AU - Bonnard, Arnaud AU - Sfeir, Rony AU - Singh, Michael AU - Yardley, Iain AU - Rikkers-Mutsaerts, Noor R. V. M. AU - van der Ent, Cornelis K. AU - Qvist, Niels AU - Cox, Des W. AU - Peters, Robert AU - Bannier, Michiel A. G. E. AU - Wessel, Lucas AU - Proesmans, Marijke AU - Stanton, Michael AU - Hannon, Edward AU - Zampoli, Marco AU - Morini, Francesco AU - Tiddens, Harm A. W. M. AU - Wijnen, René M. H. AU - Schnater, Johannes M. AB - Consensus on the optimal management of asymptomatic congenital pulmonary airway malformation (CPAM) is lacking, and comparison between studies remains difficult due to a large variety in outcome measures. We aimed to define a core outcome set (COS) for pediatric patients with an asymptomatic CPAM. An online, three-round Delphi survey was conducted in two stakeholder groups of specialized caregivers (surgeons and non-surgeons) in various European centers. Proposed outcome parameters were scored according to level of importance, and the final COS was established through consensus. A total of 55 participants (33 surgeons, 22 non-surgeons) from 28 centers in 13 European countries completed the three rounds and rated 43 outcome parameters. The final COS comprises seven outcome parameters: respiratory insufficiency, surgical complications, mass effect/mediastinal shift (at three time-points) and multifocal disease (at two time-points)<b>.</b> The seven outcome parameters included in the final COS reflect the diversity in priorities among this large group of European participants. However, we recommend the incorporation of these outcome parameters in the design of future studies, as they describe measurable and validated outcomes as well as the accepted age at measurement. DA - 2022-07-30 DB - OpenUCT DP - University of Cape Town J1 - Children LK - https://open.uct.ac.za PY - 2022 T1 - The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey TI - The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey UR - http://hdl.handle.net/11427/39147 ER - en_ZA
dc.identifier.urihttp://hdl.handle.net/11427/39147
dc.identifier.urihttps://doi.org/10.3390/children9081153
dc.identifier.vancouvercitationKersten Casper M, Hermelijn Sergei M, Mullassery D, Muthialu N, Cobanoglu N, Gartner S, et al. The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey. Children. 2022; http://hdl.handle.net/11427/39147.en_ZA
dc.publisherMultidisciplinary Digital Publishing Institute
dc.publisher.departmentDepartment of Pediatric Pulmonology
dc.publisher.facultyFaculty of Health Sciences
dc.rights.urihttps://creativecommons.org/licenses/by/4.0/
dc.sourceChildren
dc.source.journalissue8
dc.source.journalvolume9
dc.source.pagination1153
dc.source.urihttps://www.mdpi.com/journal/children
dc.titleThe Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey
dc.typeJournal Article
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