Waardenburg syndrome in childhood deafnessin Cameroon

dc.contributor.authorNoubiap, J N
dc.contributor.authorDjomou, F
dc.contributor.authorNjock, R
dc.contributor.authorToure, G B
dc.contributor.authorWonkam, A
dc.date.accessioned2016-05-17T09:55:59Z
dc.date.available2016-05-17T09:55:59Z
dc.date.issued2014
dc.date.updated2016-05-17T09:46:23Z
dc.description.abstractBackground: Waardenburg syndrome (WS) is a rare hereditary disorder essentially characterised by deafness and pigment disorders of the eyes, hair and skin. Method: Between October 2010 and December 2011, we identified six patients with WS during an aetiological survey of 582 deaf participants recruited in schools for the deaf and ear, nose and throat outpatient clinics in seven of the ten regions of Cameroon. Two classic characteristics of WS were used as diagnostic criteria: deafness and pigmentation abnormalities (heterochromia iridis, white forelock and depigmented skin patches). In addition, to identify dystopia canthorum, a sign of WS type I, we calculated the W-index. Results: WS comprised 1% of the whole sample, 7% of the genetic cases, and 50% of the genetic syndromic cases. All patients with WS had severe to profound congenital sensorineural and symmetrical hearing loss with flat audiograms. They also had pigment disorders of the eyes and the skin. In the absence of dystopia canthorum, they were all classified as having WS type II. The pedigree was suggestive of autosomal dominant inheritance in two cases, and the four others seemed to be de novo cases. Conclusion. The results suggest that WS type II is the most common syndromic form of hearing loss among Cameroonians. This has implications for retrospective genetic counselling and hearing tests for earlier management in affected families.en_ZA
dc.identifier.apacitationNoubiap, J. N., Djomou, F., Njock, R., Toure, G. B., & Wonkam, A. (2014). Waardenburg syndrome in childhood deafnessin Cameroon. <i>South African Journal of Child Health</i>, http://hdl.handle.net/11427/19694en_ZA
dc.identifier.chicagocitationNoubiap, J N, F Djomou, R Njock, G B Toure, and A Wonkam "Waardenburg syndrome in childhood deafnessin Cameroon." <i>South African Journal of Child Health</i> (2014) http://hdl.handle.net/11427/19694en_ZA
dc.identifier.citationNoubiap, J. N., Djomou, F., Njock, R., Toure, G. B., & Wonkam, A. (2014). Waardenburg syndrome in childhood deafness in Cameroon. South African Journal of Child Health, 8(1), 3-5.en_ZA
dc.identifier.issn1994-3032en_ZA
dc.identifier.ris TY - Journal Article AU - Noubiap, J N AU - Djomou, F AU - Njock, R AU - Toure, G B AU - Wonkam, A AB - Background: Waardenburg syndrome (WS) is a rare hereditary disorder essentially characterised by deafness and pigment disorders of the eyes, hair and skin. Method: Between October 2010 and December 2011, we identified six patients with WS during an aetiological survey of 582 deaf participants recruited in schools for the deaf and ear, nose and throat outpatient clinics in seven of the ten regions of Cameroon. Two classic characteristics of WS were used as diagnostic criteria: deafness and pigmentation abnormalities (heterochromia iridis, white forelock and depigmented skin patches). In addition, to identify dystopia canthorum, a sign of WS type I, we calculated the W-index. Results: WS comprised 1% of the whole sample, 7% of the genetic cases, and 50% of the genetic syndromic cases. All patients with WS had severe to profound congenital sensorineural and symmetrical hearing loss with flat audiograms. They also had pigment disorders of the eyes and the skin. In the absence of dystopia canthorum, they were all classified as having WS type II. The pedigree was suggestive of autosomal dominant inheritance in two cases, and the four others seemed to be de novo cases. Conclusion. The results suggest that WS type II is the most common syndromic form of hearing loss among Cameroonians. This has implications for retrospective genetic counselling and hearing tests for earlier management in affected families. DA - 2014 DB - OpenUCT DP - University of Cape Town J1 - South African Journal of Child Health LK - https://open.uct.ac.za PB - University of Cape Town PY - 2014 SM - 1994-3032 T1 - Waardenburg syndrome in childhood deafnessin Cameroon TI - Waardenburg syndrome in childhood deafnessin Cameroon UR - http://hdl.handle.net/11427/19694 ER - en_ZA
dc.identifier.urihttp://hdl.handle.net/11427/19694
dc.identifier.urihttp://www.sajch.org.za/index.php/SAJCH/article/view/672
dc.identifier.vancouvercitationNoubiap JN, Djomou F, Njock R, Toure GB, Wonkam A. Waardenburg syndrome in childhood deafnessin Cameroon. South African Journal of Child Health. 2014; http://hdl.handle.net/11427/19694.en_ZA
dc.languageengen_ZA
dc.publisherHealth and Medical Publishing Groupen_ZA
dc.publisher.departmentDivision of Human Geneticsen_ZA
dc.publisher.facultyFaculty of Health Sciencesen_ZA
dc.publisher.institutionUniversity of Cape Town
dc.rightsCreative Commons Attribution-NonCommercial 4.0 International (CC BY-NC 4.0)*
dc.rights.urihttp://creativecommons.org/licenses/by-nc/4.0/en_ZA
dc.sourceSouth African Journal of Child Healthen_ZA
dc.source.urihttp://www.sajch.org.za/index.php/SAJCH
dc.subject.otherWaardenburg syndrome
dc.subject.otherCameroon
dc.subject.otherAfrica
dc.subject.otherdeafness
dc.subject.othergenetic counselling
dc.titleWaardenburg syndrome in childhood deafnessin Cameroonen_ZA
dc.typeJournal Articleen_ZA
uct.type.filetypeText
uct.type.filetypeImage
uct.type.publicationResearchen_ZA
uct.type.resourceArticleen_ZA
Files
Original bundle
Now showing 1 - 1 of 1
Loading...
Thumbnail Image
Name:
Noubiap_Waardenburg_syndrome_in_2014.pdf
Size:
652.73 KB
Format:
Adobe Portable Document Format
Description:
License bundle
Now showing 1 - 1 of 1
Loading...
Thumbnail Image
Name:
license.txt
Size:
1.72 KB
Format:
Item-specific license agreed upon to submission
Description:
Collections